Factor structure of the Children's Behavior Questionnaire in children with Williams syndrome.
Williams syndrome kids show a unique four-factor temperament profile that helps spot anxiety or ADHD early.
01Research in Context
What this study did
Leyfer et al. (2012) looked at how the Children’s Behavior Questionnaire works in kids with Williams syndrome. They ran an exploratory factor analysis to find the best-fit temperament model for this group.
Parents filled out the CBQ. The team split the kids into those with and without anxiety or ADHD labels to see if scores differed.
What they found
A clean four-factor structure came out: negative affect, extraversion, effort control, and a Williams-specific sociability factor. Kids tagged with anxiety or ADHD scored higher on negative affect and lower on effort control.
How this fits with other research
Katz et al. (2018) used the same stats trick—exploratory factor analysis—to shorten the Children’s Sleep Habits Questionnaire for autistic kids and also landed on four factors. Both studies show one size does not fit all; you have to re-validate parent forms for each diagnosis.
Leaf et al. (2012) tracked IQ stability in the same Williams group. IQ stayed flat on average, yet the new CBQ factors move up or down with anxiety/ADHD status. Together they tell you: watch temperament, not just IQ, when planning supports.
Tse et al. (2021) built an 11-factor teacher scale for mainstream autistic pupils. More factors let finer targets, but Ovsanna’s four are easier to graph for parents during clinic visits.
Why it matters
If you assess a child with Williams syndrome, pull the CBQ and score the four factors. A spike on negative affect plus low effort control flags anxiety or ADHD risk so you can refer early. Pair these scores with the stable IQ data from Leaf et al. (2012) to write goals that focus on self-regulation, not academic rate. Share the four-factor profile with teachers and parents; it is simple and shows why a kid might look friendly yet fall apart when plans change.
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02At a glance
03Original abstract
To examine the factor structure of temperament in 5-10-year-olds with Williams syndrome, an exploratory factor analysis was conducted on the responses of parents of 192 children on the children's behavior questionnaire. Four factors were identified. Two corresponded to factors reported for typically developing children: effortful control and extraversion/surgency and two corresponded to the temperament constructs of withdrawal/inhibition and irritability/frustration and activity, observed in typically developing infants. Parents of 109 of the 192 participants also completed the anxiety disorders interview schedule, parent version. Children with an anxiety disorder other than specific phobia differed significantly from children without an anxiety disorder on all factors except extraversion/surgency. Children with attention deficit hyperactivity disorder (ADHD) differed significantly from children without ADHD on effortful control and extraversion/surgency.
Journal of autism and developmental disorders, 2012 · doi:10.1002/ajmg.1320360321